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Inicio Revista Colombiana de Reumatología (English Edition) Use of rituximab for granulomatosis with polyangiitis-associated peripheral ulce...
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Case Report
Use of rituximab for granulomatosis with polyangiitis-associated peripheral ulcerative keratitis
Uso de rituximab en queratopatía ulcerativa periférica y uveítis secundaria a granulomatosis con poliangeítis
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José David Paulo Trujilloa, Juan Carlos Mejía Turizob,
Corresponding author
jcmturizo@hotmail.com

Corresponding author.
a Servicio de Oftalmología, Hospital Pablo Tobón Uribe, Medellín, Colombia
b Oftalmología, Universidad Pontificia Bolivariana, Medellín, Colombia
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Received 24 June 2016. Accepted 26 August 2016
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Abstract

A 31-year-old female, presented with polyarthralgia, asymmetrical polyarthritis, fever, vasculitis skin lesions, together with decreased visual acuity in the right eye with severe peripheral corneal melting, peripheral ulcerative keratitis, fibrin hypopyon and posterior synechiae. Given the clinical and paraclinical findings with positive C-ANCA (anti-neutrophil cytoplasmic antibodies), the patient was diagnosed with granulomatosis with polyangiitis with ocular (corneal melting, peripheral ulcerative keratitis and uveitis), and systemic involvement. Treatment was started with methylprednisolone and cyclophosphamide, but due to poor control, Rituximab was subsequently administered, with medical improvement.

Keywords:
Granulomatosis with polyangiitis
Wegener granulomatosis
Cornea
Peripheral ulcerative keratitis
Rituximab
Uveitis
Resumen

Mujer de 31 años con cuadro de poliartralgias, poliartritis asimétrica, fiebre, lesiones vasculíticas en piel, asociado a disminución de agudeza visual en ojo derecho, el cual presentaba compromiso corneal con adelgazamiento periférico severo, queratitis ulcerativa periférica, hipopión de fibrina y sinequias posteriores. Ante el cuadro clínico y paraclínicos con C-ANCA positivos, se realiza el diagnóstico de granulomatosis con poliangeítis con compromiso ocular (adelgazamiento corneal, queratitis ulcerativa periférica, uveítis) y sistémico. Se inicia tratamiento con metilprednisolona y ciclofosfamida con poco control, por lo que se inicia rituximab sistémico, evolucionando hacia la mejoría.

Palabras clave:
Granulomatosis con poliangeítis
Granulomatosis de Wegener
Córnea
Queratitis ulcerativa periférica
Rituximab
Uveítis

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